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Published in: BMC Cardiovascular Disorders 1/2024

Open Access 01-12-2024 | Angiography | Case Report

Adult-type anomalous origin of the left coronary artery from the pulmonary artery and right coronary-right atrial fistula: a case report

Authors: Hao Luo, Ofe Eugene Kwaku, Yinglong Lai, Rongchuan Yue

Published in: BMC Cardiovascular Disorders | Issue 1/2024

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Abstract

Background

Anomalous origin of the left coronary artery from the pulmonary artery (ALCAPA) is a rare congenital cardiac anomaly, mortality rates in infancy reach approximately 90%, with only a small number of patients surviving into adulthood, therefore, most of the literature reports mainly focus on infantile type.

Case presentation

A 55-year-old female was admitted due to persistent repeated chest pain experienced and had worsened for unknown reasons. Color doppler echocardiography, coronary computed tomographic angiography, and coronary angiography confirmed the diagnosis of ALCAPA and concurrent right coronary artery-right atrial fistula. The symptoms of chest pain exhibited notable improvement subsequent to corrective surgery for the anomalous origin of the coronary artery.

Conclusions

This report shows an unique case of ALCAPA in an adult patient, characterizing the condition’s combination with a right coronary-right atrial fistula, and it is prone to misdiagnosis and misdiagnosis. We aim to provide valuable insights for clinical diagnosis and treatment of ALCAPA.
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Metadata
Title
Adult-type anomalous origin of the left coronary artery from the pulmonary artery and right coronary-right atrial fistula: a case report
Authors
Hao Luo
Ofe Eugene Kwaku
Yinglong Lai
Rongchuan Yue
Publication date
01-12-2024
Publisher
BioMed Central
Published in
BMC Cardiovascular Disorders / Issue 1/2024
Electronic ISSN: 1471-2261
DOI
https://doi.org/10.1186/s12872-023-03686-x

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