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Published in: BMC Pulmonary Medicine 1/2018

Open Access 01-12-2018 | Case report

Chyloptysis with chylopericardium, a rare case and mini-review

Authors: Xuming Luo, Zhuhua Zhang, ShiQiang Wang, XianDong Gu, Xiongbiao Wang

Published in: BMC Pulmonary Medicine | Issue 1/2018

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Abstract

Background

Chyloptysis is reflux of chyle into the lungs and is a rare manifestation of primary chylous disorders.

Case presentation

Over 29 months, on the basis of x-rays, a 33-year-old female was repeatedly misdiagnosed with recurrent right-sided pneumonia; her symptoms included a recurrent cough, the appearance of cheese-like sputum, and diffuse pulmonary exudates. There was a history that abundant fluid in the pericardium was confirmed with echocardiography to have been present and asymptomatic for 4 years. Lymphangiography and surgery confirmed that the terminal portion of the thoracic duct was compressed by thick fibrous tissue and the vascular sheath of the internal jugular vein. Chyloptysis caused by high peribronchial lymphatic pressure was diagnosed and surgical intervention relieved the symptoms.

Conclusion

Chyloptysis is rare and easy to misdiagnose but is a typical symptom of chylous reflux syndrome.
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Metadata
Title
Chyloptysis with chylopericardium, a rare case and mini-review
Authors
Xuming Luo
Zhuhua Zhang
ShiQiang Wang
XianDong Gu
Xiongbiao Wang
Publication date
01-12-2018
Publisher
BioMed Central
Published in
BMC Pulmonary Medicine / Issue 1/2018
Electronic ISSN: 1471-2466
DOI
https://doi.org/10.1186/s12890-018-0583-y

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