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Published in: Clinical Journal of Gastroenterology 3/2020

01-06-2020 | Computed Tomography | Case Report

A rare case of Goodpasture syndrome concomitant with bleeding jejunal Dieulafoy’s lesion

Authors: Hideaki Kawabata, Yukino Kawakatsu, Daiki Sone, Katsutoshi Yamaguchi, Naonori Inoue, Yuki Ueda, Yuji Okazaki, Misuzu Hitomi, Masatoshi Miyata, Shigehiro Motoi, Masayasu Nishimura, Tsutomu Shikano

Published in: Clinical Journal of Gastroenterology | Issue 3/2020

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Abstract

An 81-year-old man was diagnosed with Goodpasture syndrome (GS) because he met the criteria of positive anti-GBM antibodies, rapid progressive glomerulonephritis and pulmonary hemorrhage. After starting plasmapheresis and steroid pulse therapy, he experienced tarry stool and contrast-enhanced CT revealed an aneurysmal finding in the jejunum. Paroral enteroscopy showed a jejunal Dieulafoy’s lesion (DL) with gush-out hemorrhage. Hemostasis was successfully achieved by hemoclipping, and he then experienced no re-bleeding events. GS can present as a jejunal DL, and contrast-enhanced CT is useful for investigating the etiology and site of small intestinal bleeding, which can lead to smooth, effective endoscopic hemostasis.
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Metadata
Title
A rare case of Goodpasture syndrome concomitant with bleeding jejunal Dieulafoy’s lesion
Authors
Hideaki Kawabata
Yukino Kawakatsu
Daiki Sone
Katsutoshi Yamaguchi
Naonori Inoue
Yuki Ueda
Yuji Okazaki
Misuzu Hitomi
Masatoshi Miyata
Shigehiro Motoi
Masayasu Nishimura
Tsutomu Shikano
Publication date
01-06-2020
Publisher
Springer Singapore
Published in
Clinical Journal of Gastroenterology / Issue 3/2020
Print ISSN: 1865-7257
Electronic ISSN: 1865-7265
DOI
https://doi.org/10.1007/s12328-019-01078-3

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