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Published in: BMC Cardiovascular Disorders 1/2021

Open Access 01-12-2021 | Arteriovenous Fistula | Case report

Left ventricular inflow obstruction due to a coronary arteriovenous fistula: a paediatric case report

Authors: Ayako Chida-Nagai, Hirokuni Yamazawa, Takao Tsujioka, Kota Taniguchi, Osamu Sasaki, Gaku Izumi, Nobuyasu Kato, Atsuhito Takeda

Published in: BMC Cardiovascular Disorders | Issue 1/2021

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Abstract

Background

We report a rare case of left ventricular inflow obstruction from a branch of the left circumflex coronary artery to the right atrium caused by a coronary arteriovenous fistula (CAVF) in a young Japanese male child.

Case presentation

The patient was diagnosed with CAVF following a heart murmur shortly after birth. The left-to-right shunt caused right ventricular volume overload and pulmonary congestion. An emergency surgical intervention was performed for the CAVF on day 6 after birth. However, by 5 years of age, his left ventricular inflow obstruction worsened. We found an abnormal blood vessel originating from the proximal part of a branch of the left circumflex coronary artery, circling the outside of the mitral valve annulus along the medial side of the coronary sinus. As the child gets older, the blood inflow into the left ventricle might get restricted further, resulting in left-sided heart failure.

Conclusion

Our findings suggest that even after CAVF closure surgery, it is essential to monitor for complications caused by progressive dilatation of a persistent CAVF.
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Metadata
Title
Left ventricular inflow obstruction due to a coronary arteriovenous fistula: a paediatric case report
Authors
Ayako Chida-Nagai
Hirokuni Yamazawa
Takao Tsujioka
Kota Taniguchi
Osamu Sasaki
Gaku Izumi
Nobuyasu Kato
Atsuhito Takeda
Publication date
01-12-2021
Publisher
BioMed Central
Published in
BMC Cardiovascular Disorders / Issue 1/2021
Electronic ISSN: 1471-2261
DOI
https://doi.org/10.1186/s12872-021-02190-4

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