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Published in: Journal of Medical Case Reports 1/2015

Open Access 01-12-2015 | Case report

Variant angina in moyamoya disease – a correlative etiology and different presentation: a case report

Authors: Woong Choi, Yu Na Kim, Kyung-Hee Kim

Published in: Journal of Medical Case Reports | Issue 1/2015

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Abstract

Introduction

Moyamoya disease is characterized by progressive steno-occlusive changes of the distal internal carotid and developed collateral vasculature, so called ‘moyamoya’ vessels at the base of the brain. Variant angina is a rare occurrence in patients with moyamoya disease.

Case presentation

Here we report the case of a 41-year-old Korean woman who developed chest pain after indirect revascularization surgery of moyamoya disease. A treadmill test and an exercise stress echocardiograph showed positive results, but there was no significant major coronary arteries stenosis. Suspicious of vasospasm, we conducted an ergonovine spasm stimulation test, which demonstrated tight stenosis of her proximal left anterior descending artery. At the site of spasm, intravascular ultrasound virtual histology showed intraluminal fibrous plaque.

Conclusion

Physicians who follow up patients with moyamoya disease would need to be aware of the possibility of cardiac ischemia as well as neurological manifestations.
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Metadata
Title
Variant angina in moyamoya disease – a correlative etiology and different presentation: a case report
Authors
Woong Choi
Yu Na Kim
Kyung-Hee Kim
Publication date
01-12-2015
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2015
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/s13256-015-0537-4

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