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Published in: BMC Ophthalmology 1/2015

Open Access 01-12-2015 | Case report

Profound hypotony maculopathy in a first episode of bilateral idiopathic acute anterior uveitis

Authors: Matthew R. Edmunds, Simon N. Madge

Published in: BMC Ophthalmology | Issue 1/2015

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Abstract

Background

We report a case of a HLA-B27 negative patient presenting with severe, bilateral, idiopathic acute anterior uveitis with acute hypotony and hypotony maculopathy as their first uveitic episode.

Case presentation

Within a week of onset of her first episode of acute anterior uveitis, a 45 year-old Caucasian lady developed profound ocular hypotony with unrecordable intraocular pressures, reduced vision and choroidal folds. All investigations were negative. Uveitic hypotony responded slowly to corticosteroids – intravenous, oral and topical – with normalization of intraocular pressure and resolution of choroidal folds after two months. Anterior uveitis and hypotony have not returned with six months of follow-up.

Conclusion

Bilateral, profound hypotony maculopathy may present acutely in idiopathic acute anterior uveitis, may be slow to respond to treatment and should be considered as a cause of vision loss in patients with this condition.
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Metadata
Title
Profound hypotony maculopathy in a first episode of bilateral idiopathic acute anterior uveitis
Authors
Matthew R. Edmunds
Simon N. Madge
Publication date
01-12-2015
Publisher
BioMed Central
Published in
BMC Ophthalmology / Issue 1/2015
Electronic ISSN: 1471-2415
DOI
https://doi.org/10.1186/s12886-015-0105-0

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