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Published in: BMC Neurology 1/2014

Open Access 01-12-2014 | Case report

Neurotrophic keratopathy due to dorsolateral medullary infarction (Wallenberg Syndrome): case report and literature review

Authors: Songdi Wu, Ningning Li, Feng Xia, Kastytis Sidlauskas, Xuemei Lin, Yihua Qian, Wei Gao, Qinlu Zhang

Published in: BMC Neurology | Issue 1/2014

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Abstract

Background

Dorsolateral medullary infarction (Wallenberg Syndrome) is rare in clinical practice; however, the subsequent corneal lesions are more uncommon. To our knowledge, only one such case was previously reported. We report a similar case with successful treatment and recovery, and analyse both cases to address the clinical features and outcomes of such syndrome.

Case presentation

A 43-year-old male presented with neurotrophic keratopathy one month after sustaining dorsolateral medullary infarction. The patient underwent amniotic membrane transplantation twice. Two-year follow-up observation revealed changes in nerve fibers and epithelial cells of corneal by laser confocal microscopy.

Conclusion

By studying both cases, we confirm that neurotrophic keratopathy could be as a delayed-onset complication of Wallenberg syndrome. The recognition that neurotrophic keratopathy can follow dorsolateral medullary infarction could prevent the clinical misdiagnosis.
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Metadata
Title
Neurotrophic keratopathy due to dorsolateral medullary infarction (Wallenberg Syndrome): case report and literature review
Authors
Songdi Wu
Ningning Li
Feng Xia
Kastytis Sidlauskas
Xuemei Lin
Yihua Qian
Wei Gao
Qinlu Zhang
Publication date
01-12-2014
Publisher
BioMed Central
Published in
BMC Neurology / Issue 1/2014
Electronic ISSN: 1471-2377
DOI
https://doi.org/10.1186/s12883-014-0231-y

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