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Published in: BMC Urology 1/2023

Open Access 08-07-2023 | Disease of the Adrenal Glands | Case Report

Simultaneous adrenal and retroperitoneal myelolipoma resected by laparoscopic surgery: a challenging case

Authors: Hooman Kamran, Abdolreza Haghpanah, Mohammad Hossein Dabbaghmanesh, Lorenzo Defidio, Maryam Bazrafkan, Anahita Dehghani, Mehdi Shirazi, Nima Naderi, Amirreza Dehghanian

Published in: BMC Urology | Issue 1/2023

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Abstract

Background

Myelolipoma is a benign neoplasm of the adrenal cortex, composed of fat and hematopoietic cells. Although myelolipoma is benign, differentiation from adrenocortical cancer may be difficult. The presence of adrenal and extra-adrenal myelolipomas simultaneously is sporadic, making it a challenging case, especially when the preoperative diagnosis is ambiguous.

Case presentation

A 65-year-old man was referred to our clinic due to a mass in the adrenal fossa. In the abdominopelvic computed tomography (CT), a well-circumscribed fat-containing 78 × 61 × 65 mm bi-lobulated mass was reported in the left adrenal fossa. The first differential diagnosis was myelolipoma. The patient was then referred to our clinic for a mass excision. He was asymptomatic and was scheduled to undergo laparoscopic-assisted adrenalectomy. After adrenalectomy and mass dissection, surprisingly, another mass was detected in the retroperitoneal area. The second mass was also dissected. The final diagnosis was myelolipoma for both masses. The patient has been symptom-free for nine months after the operation.

Conclusion

Simultaneous adrenal and extra-adrenal myelolipoma should be considered as one of the differential diagnoses. However, because this situation is extremely rare, the probability of malignancy should be highly regarded, and we suggest an obsessive approach when approaching this condition. It is essential to manage these cases on a case-by-case basis and tailor the management concerning intraoperative biopsy, the intraoperative appearance of tumors, and the location of extra-adrenal masses.
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Metadata
Title
Simultaneous adrenal and retroperitoneal myelolipoma resected by laparoscopic surgery: a challenging case
Authors
Hooman Kamran
Abdolreza Haghpanah
Mohammad Hossein Dabbaghmanesh
Lorenzo Defidio
Maryam Bazrafkan
Anahita Dehghani
Mehdi Shirazi
Nima Naderi
Amirreza Dehghanian
Publication date
08-07-2023
Publisher
BioMed Central
Published in
BMC Urology / Issue 1/2023
Electronic ISSN: 1471-2490
DOI
https://doi.org/10.1186/s12894-023-01288-5

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