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Published in: Indian Journal of Thoracic and Cardiovascular Surgery 4/2018

01-10-2018 | Case report

Congenital cystic adenomatoid malformation of the lung in adults: report of two cases and review of the literature

Authors: Sidharth Garg, Rana Sandeep Singh, Harkant Singh

Published in: Indian Journal of Thoracic and Cardiovascular Surgery | Issue 4/2018

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Abstract

Congenital cystic adenomatoid malformation (CCAM) is characterized by adenomatoid proliferation of bronchiole-like structures and cysts formation. It isan uncommon cause of respiratory distress in infants. Most common presentation is in first two years of life with complaints of respiratory distress.Presentation in adulthood is rare. Surgical intervention is the mainstay treatment.We describe two cases of atypical CCAM presenting in adulthood with past history of tuberculosis. To our knowledge only one case of CCAM with tuberculosis has been reported in literature.
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Metadata
Title
Congenital cystic adenomatoid malformation of the lung in adults: report of two cases and review of the literature
Authors
Sidharth Garg
Rana Sandeep Singh
Harkant Singh
Publication date
01-10-2018
Publisher
Springer Singapore
Published in
Indian Journal of Thoracic and Cardiovascular Surgery / Issue 4/2018
Print ISSN: 0970-9134
Electronic ISSN: 0973-7723
DOI
https://doi.org/10.1007/s12055-018-0650-2

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