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Published in: Journal of Inherited Metabolic Disease 3/2015

01-05-2015 | Original Article

Treatment options for lactic acidosis and metabolic crisis in children with mitochondrial disease

Authors: Katharina Danhauser, Jan A. M. Smeitink, Peter Freisinger, Wolfgang Sperl, Hemmen Sabir, Berit Hadzik, Ertan Mayatepek, Eva Morava, Felix Distelmaier

Published in: Journal of Inherited Metabolic Disease | Issue 3/2015

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Abstract

The mitochondrial pyruvate oxidation route is a tightly regulated process, which is essential for aerobic cellular energy production. Disruption of this pathway may lead to severe neurometabolic disorders with onset in early childhood. A frequent finding in these patients is acute and chronic lactic acidemia, which is caused by increased conversion of pyruvate via the enzyme lactate dehydrogenase. Under stable clinical conditions, this process may remain well compensated and does not require specific therapy. However, especially in situations with altered energy demands, such as febrile infections or longer periods of fasting, children with mitochondrial disorders have a high risk of metabolic decompensation with exacerbation of hyperlactatemia and severe metabolic acidosis. Unfortunately, no controlled studies regarding therapy of this critical condition are available and clinical outcome is often unfavorable. Therefore, the aim of this review was to formulate expert-based suggestions for treatment of these patients, including dietary recommendations, buffering strategies and specific drug therapy. However, it is important to keep in mind that a specific therapy for the underlying metabolic cause in children with mitochondrial diseases is usually not available and symptomatic therapy especially of severe lactic acidosis has its ethical limitations.
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Metadata
Title
Treatment options for lactic acidosis and metabolic crisis in children with mitochondrial disease
Authors
Katharina Danhauser
Jan A. M. Smeitink
Peter Freisinger
Wolfgang Sperl
Hemmen Sabir
Berit Hadzik
Ertan Mayatepek
Eva Morava
Felix Distelmaier
Publication date
01-05-2015
Publisher
Springer Netherlands
Published in
Journal of Inherited Metabolic Disease / Issue 3/2015
Print ISSN: 0141-8955
Electronic ISSN: 1573-2665
DOI
https://doi.org/10.1007/s10545-014-9796-2

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Live Webinar | 27-06-2024 | 18:00 (CEST)

Keynote webinar | Spotlight on medication adherence

Live: Thursday 27th June 2024, 18:00-19:30 (CEST)

WHO estimates that half of all patients worldwide are non-adherent to their prescribed medication. The consequences of poor adherence can be catastrophic, on both the individual and population level.

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