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Published in: European Spine Journal 3/2018

01-07-2018 | Case Report

Myelopathy associated with instability consequent to resection of ossification of anterior longitudinal ligament in DISH

Authors: Man-Kyu Park, Kyoung-Tae Kim, Dae-Chul Cho, Joo-Kyung Sung

Published in: European Spine Journal | Special Issue 3/2018

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Abstract

Purpose

The presence of prominent OALL (ossification of anterior longitudinal ligament) in the anterior cervical spine has been implicated as a cause of dysphagia. Surgical resection of the OALL is considered effective for the management of diffuse idiopathic skeletal hyperostosis (DISH)-related dysphagia. Although many reports have been published on DISH-related dysphagia, no cases of postoperative cervical instability have been reported thus far. We present a case in which the patient developed myelopathy associated with instability consequent to resection of OALL in DISH.

Methods

A 62-year-old man presented with progressive dysphagia that persisted for a year. The patient’s symptoms were successfully resolved by resection of OALL. Five years after the surgery, the dysphagia resurfaced and was found to be caused by the regrowth of the OALL. A repeat surgery was performed, and the dysphagia disappeared. Eleven months after the second surgery, he visited the hospital with progressive quadriparesis and pain in the cervical region.

Results

Nine-month follow-up radiologic study revealed cervical instability at the level of C5–6 resulting in myelopathy. The patient underwent decompressive laminectomy and posterior fusion surgery.

Conclusion

Surgical resection of DISH-related dysphagia typically yields excellent outcomes, but our experience in this case highlights the possibility of OALL regrowth and subsequent cervical instability after resection of OALL.
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Metadata
Title
Myelopathy associated with instability consequent to resection of ossification of anterior longitudinal ligament in DISH
Authors
Man-Kyu Park
Kyoung-Tae Kim
Dae-Chul Cho
Joo-Kyung Sung
Publication date
01-07-2018
Publisher
Springer Berlin Heidelberg
Published in
European Spine Journal / Issue Special Issue 3/2018
Print ISSN: 0940-6719
Electronic ISSN: 1432-0932
DOI
https://doi.org/10.1007/s00586-017-5236-y

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