Skip to main content
Top
Published in: Pediatric Cardiology 3/2013

01-03-2013 | Case Report

A Rare Case of Left Lung Hypoplasia Associated With Congenital Pulmonary Artery Aneurysm and Ventricular Septal Defect

Authors: Amar N. Patnaik, Ramachandra Barik, Sagar Babu, A. S. Gullati

Published in: Pediatric Cardiology | Issue 3/2013

Login to get access

Abstract

This report describes a 3-year-old boy who presented with hemoptysis and a history of congenital heart disease detected at the age of 3 months. Clinical and laboratory evaluation showed a large true congenital pulmonary artery aneurysm of the left main pulmonary artery occupying the entire left hemithorax and two small aneurysms in the right lung. In addition, a restricted ventricular septal defect was detected. It was evident on clinical and histologic grounds that the multiple aneurysms seen in this child stemmed from congenital weakness of the arterial wall in conjunction with increased pulmonary blood flow and elevated pulmonary artery pressure.
Literature
1.
go back to reference Boyd LJ, Mc Gavach TH (1939) Aneurysm of the pulmonary artery. Am Heart J 18:562–578CrossRef Boyd LJ, Mc Gavach TH (1939) Aneurysm of the pulmonary artery. Am Heart J 18:562–578CrossRef
2.
3.
go back to reference Dayioglu E, Sever K, Basaran M, Kafali E, Ugurlucan M et al (2004) Idiopathic pulmonary artery aneurysm. Indian J Thorac Cardiovasc Surg 20:140–141CrossRef Dayioglu E, Sever K, Basaran M, Kafali E, Ugurlucan M et al (2004) Idiopathic pulmonary artery aneurysm. Indian J Thorac Cardiovasc Surg 20:140–141CrossRef
4.
go back to reference Deterling RA Jr, Clagett OT (1947) Aneurysm of pulmonary artery; review of the literature and report of a case. Am Heart J 34:471–499PubMedCrossRef Deterling RA Jr, Clagett OT (1947) Aneurysm of pulmonary artery; review of the literature and report of a case. Am Heart J 34:471–499PubMedCrossRef
5.
go back to reference Garcia-Rinaldi R, Howell JF (1976) Aneurysm of the main pulmonary artery: long-term survival after aneurysmorrhaphy and closure of a ventricular septal defect. Ann Thorac Surg 21:180–183PubMedCrossRef Garcia-Rinaldi R, Howell JF (1976) Aneurysm of the main pulmonary artery: long-term survival after aneurysmorrhaphy and closure of a ventricular septal defect. Ann Thorac Surg 21:180–183PubMedCrossRef
6.
go back to reference Gorodezky M, Maroto JM, Mota J, Cardenas M, Contreras R (1974) Mycotic aneurysms of the pulmonary artery. Chest 66:214–216PubMedCrossRef Gorodezky M, Maroto JM, Mota J, Cardenas M, Contreras R (1974) Mycotic aneurysms of the pulmonary artery. Chest 66:214–216PubMedCrossRef
7.
go back to reference Kauffman SL, Lynfield J, Hennigar GR (1967) Mycotic aneurysms of the intrapulmonary arteries. Circulation 35:90–99PubMedCrossRef Kauffman SL, Lynfield J, Hennigar GR (1967) Mycotic aneurysms of the intrapulmonary arteries. Circulation 35:90–99PubMedCrossRef
8.
go back to reference Lalitha P, Reddy MB, Jagannath KR (2009) Idiopathic multiple pulmonary artery aneurysms. Pak J Radiol 19:83–85 Lalitha P, Reddy MB, Jagannath KR (2009) Idiopathic multiple pulmonary artery aneurysms. Pak J Radiol 19:83–85
9.
go back to reference Lee K, Shin T, Choi J, Kim Y (2008) Percutaneous injection therapy for a peripheral pulmonary artery pseudoaneurysm after failed transcatheter coil embolization. Cardiovasc Intervent Radiol 31:1038–1041PubMedCrossRef Lee K, Shin T, Choi J, Kim Y (2008) Percutaneous injection therapy for a peripheral pulmonary artery pseudoaneurysm after failed transcatheter coil embolization. Cardiovasc Intervent Radiol 31:1038–1041PubMedCrossRef
10.
go back to reference Ramakrishnan S, Kothari SS, Sharma S (2010) Massive left pulmonary artery pseudoaneurysm in a young child. J Am Coll Cardiol Intv 3:362–363 Ramakrishnan S, Kothari SS, Sharma S (2010) Massive left pulmonary artery pseudoaneurysm in a young child. J Am Coll Cardiol Intv 3:362–363
11.
go back to reference Tunaci M, Ozkorkmaz B, Tunaci A, Gul A, Engin G, Acunas B (1999) CT findings of pulmonary artery aneurysms during treatment for Behcet’s disease. Am J Roentgenol 172:729–733CrossRef Tunaci M, Ozkorkmaz B, Tunaci A, Gul A, Engin G, Acunas B (1999) CT findings of pulmonary artery aneurysms during treatment for Behcet’s disease. Am J Roentgenol 172:729–733CrossRef
12.
go back to reference Vistarini N, Aubert S, Gandjbakhch I, Pavie A (2007) Surgical treatment of a pulmonary artery aneurysm. Eur J Cardiothorac Surg 31:1139–1141PubMedCrossRef Vistarini N, Aubert S, Gandjbakhch I, Pavie A (2007) Surgical treatment of a pulmonary artery aneurysm. Eur J Cardiothorac Surg 31:1139–1141PubMedCrossRef
13.
go back to reference Wilson N, Mcleod K, Hallworth D (2000) Images in cardiology: exclusion of a pulmonary artery aneurysm using a covered stent. Heart 83:438PubMedCrossRef Wilson N, Mcleod K, Hallworth D (2000) Images in cardiology: exclusion of a pulmonary artery aneurysm using a covered stent. Heart 83:438PubMedCrossRef
Metadata
Title
A Rare Case of Left Lung Hypoplasia Associated With Congenital Pulmonary Artery Aneurysm and Ventricular Septal Defect
Authors
Amar N. Patnaik
Ramachandra Barik
Sagar Babu
A. S. Gullati
Publication date
01-03-2013
Publisher
Springer-Verlag
Published in
Pediatric Cardiology / Issue 3/2013
Print ISSN: 0172-0643
Electronic ISSN: 1432-1971
DOI
https://doi.org/10.1007/s00246-012-0338-0

Other articles of this Issue 3/2013

Pediatric Cardiology 3/2013 Go to the issue