Skip to main content
Top
Published in: Pediatric Cardiology 1/2008

01-01-2008 | Case Report

A Case of Plastic Bronchitis Presenting 9 Years After Fontan

Authors: H. J. Zaccagni, L. Kirchner, J. Brownlee, K. Bloom

Published in: Pediatric Cardiology | Issue 1/2008

Login to get access

Abstract

A 15-year-old boy with hypoplastic left heart syndrome experienced plastic bronchitis 9 years after completion of a nonfenestrated lateral tunnel Fontan. Despite cardiac catheterization with coil embolization of collateral vessels and initiation of a pulmonary toilet regimen, including aerosolized tissue plasminogen activator, he continued to expectorate large acellular-mucinous casts. Finally, after optimization of cardiac function with the addition of carvedilol, the expectorated casts decreased in number. This report reviews pathophysiology of plastic bronchitis cast formation and therapy in the context of this late presentation after Fontan.
Literature
1.
go back to reference Barber BJ, Burch GH, Tripple D, Balaji S (2004) Resolution of plastic bronchitis with atrial pacing in a patient with Fontan physiology. Pediatr Cardiol 25:73–76PubMedCrossRef Barber BJ, Burch GH, Tripple D, Balaji S (2004) Resolution of plastic bronchitis with atrial pacing in a patient with Fontan physiology. Pediatr Cardiol 25:73–76PubMedCrossRef
2.
go back to reference Bettman M (1902) Report of a case of fibrinous bronchitis, with a review of all the cases of the literature. Am J Med Sci 123:304–329CrossRef Bettman M (1902) Report of a case of fibrinous bronchitis, with a review of all the cases of the literature. Am J Med Sci 123:304–329CrossRef
3.
go back to reference Brogan TV, Finn LS, Pyskaty DJ Jr, Redding GJ, Ricker D, Inglis A, Gibson RL (2002) Plastic bronchitis in children: A case series and review of the medical literature. Pediatr Pulmonol 34:482–487PubMedCrossRef Brogan TV, Finn LS, Pyskaty DJ Jr, Redding GJ, Ricker D, Inglis A, Gibson RL (2002) Plastic bronchitis in children: A case series and review of the medical literature. Pediatr Pulmonol 34:482–487PubMedCrossRef
4.
go back to reference Hug M, Ersch J, Moenkhoff M, Burger R, Fanconi S, Bauersfeld U (2001) Chylous bronchial casts after Fontan operation. Circulation 103:1031PubMed Hug M, Ersch J, Moenkhoff M, Burger R, Fanconi S, Bauersfeld U (2001) Chylous bronchial casts after Fontan operation. Circulation 103:1031PubMed
5.
go back to reference Madsen P, Shah SA, Rubin BK (2005) Plastic bronchitis: New insights and a classification scheme. Paediatr Respir Rev 6:292–300PubMedCrossRef Madsen P, Shah SA, Rubin BK (2005) Plastic bronchitis: New insights and a classification scheme. Paediatr Respir Rev 6:292–300PubMedCrossRef
8.
go back to reference Quasney M, Orman K, Thompson J, Ring J, Salim M, Schoumacher RA, Watson D, Novick W, Deitcher SR, Joyner R (2000) Plastic bronchitis occurring late ofter Fontan procedure: Treatment with aerosolized urokinase. Crit Care Med 28:2107–2111PubMedCrossRef Quasney M, Orman K, Thompson J, Ring J, Salim M, Schoumacher RA, Watson D, Novick W, Deitcher SR, Joyner R (2000) Plastic bronchitis occurring late ofter Fontan procedure: Treatment with aerosolized urokinase. Crit Care Med 28:2107–2111PubMedCrossRef
9.
go back to reference Seear M (2001) Acellular bronchial casts in children after cardiac surgery. Crit Care Med 29:465–466PubMedCrossRef Seear M (2001) Acellular bronchial casts in children after cardiac surgery. Crit Care Med 29:465–466PubMedCrossRef
10.
go back to reference Seear M, Hui H, Magee F, Bonn D, Cutz E (1997) Bronchial casts in children: A proposed classification based on nine cases and review of the literature. Am J Respir Crit Care Med 155:364–370PubMed Seear M, Hui H, Magee F, Bonn D, Cutz E (1997) Bronchial casts in children: A proposed classification based on nine cases and review of the literature. Am J Respir Crit Care Med 155:364–370PubMed
Metadata
Title
A Case of Plastic Bronchitis Presenting 9 Years After Fontan
Authors
H. J. Zaccagni
L. Kirchner
J. Brownlee
K. Bloom
Publication date
01-01-2008
Publisher
Springer-Verlag
Published in
Pediatric Cardiology / Issue 1/2008
Print ISSN: 0172-0643
Electronic ISSN: 1432-1971
DOI
https://doi.org/10.1007/s00246-007-9127-6

Other articles of this Issue 1/2008

Pediatric Cardiology 1/2008 Go to the issue