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Published in: Journal of Cardiothoracic Surgery 1/2019

Open Access 01-12-2019 | Case report

Aberrant pancreatic tissue in a giant mediastinal cyst: an uncommon entity

Authors: Josiah Miner Njem, Benjamin Ugwu, John Collins, Innocent Emmanuel, Ojile Akpa Philip, John Awodi

Published in: Journal of Cardiothoracic Surgery | Issue 1/2019

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Abstract

Background

Heterotopia of pancreatic tissue in the thorax and mediastinum is uncommon, although, a common developmental anomaly in the gastrointestinal tract where the aberrant tissue is a component of gastrointestinal duplication cysts, intralobular pulmonary sequestration or teratomas.

Case presentation

We report a case of an ectopic pancreas located in a giant mediastinal cyst in a 2-year old girl who presented with severe dyspnoea due to external compression of the intra-thoracic structures, mainly the right main bronchus. Surgical resection was carried out with complete relief of symptoms. The cyst was confirmed histopathologically to contain pancreatic tissue. Literature review showed that this is an uncommon presentation hence the need to report the case.

Conclusion

Heterotopia of the pancreas although, an uncommon occurrence in the thorax and mediastinum, should be considered when dealing with cystic lesions of the mediastinum and surgery plays an important role in its management.

Trial registration

JUTH/DCS/ADM/127/XXV/203. Registered 2nd September 2018.
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Metadata
Title
Aberrant pancreatic tissue in a giant mediastinal cyst: an uncommon entity
Authors
Josiah Miner Njem
Benjamin Ugwu
John Collins
Innocent Emmanuel
Ojile Akpa Philip
John Awodi
Publication date
01-12-2019
Publisher
BioMed Central
Published in
Journal of Cardiothoracic Surgery / Issue 1/2019
Electronic ISSN: 1749-8090
DOI
https://doi.org/10.1186/s13019-019-0955-2

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