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Published in: Journal of Medical Case Reports 1/2021

Open Access 01-12-2021 | Osteomalacia | Case report

Ethmoid glomangioma and oncogenic osteomalacia: a case report

Authors: Camila R. Muniz, Gabriela A. M. Bezerra, Viviane C. da Silva, Priscilla M. F. Aguiar, Gunter Gerson, Catarina B. D’Alva, André A. A. Nunes

Published in: Journal of Medical Case Reports | Issue 1/2021

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Abstract

Background

Glomangioma is a benign tumor of mesenchymal origin, derived from the glomus body. It is responsible for the thermal regulation of the dermis. The occurrence of oncogenic osteomalacia related to glomangioma is rare. Only two cases have been reported thus far.

Case presentation

A 32-year-old female, Brazilian, presented diffuse pain, during pregnancy, that developed progressively, limiting her mobility. Imaging showed a femoral neck fracture, and rheumatological laboratory examination showed hypophosphatemia. Also, the patient reported episodes of epistaxis during childhood and recurrence along with progressively right nasal obstruction. Endoscopic resection of the tumor was performed, and immunohistochemistry was conclusive for glomangioma. This case report describes the third case in which endonasal endoscopic surgery resulted in a favorable outcome.

Conclusion

This case of glomangioma-induced oncogenic osteomalacia suggests that surgeons and clinicians should consider sinonasal tumors as a differential diagnosis of osteomalacia, and endonasal endoscopic surgery should be a possible curative resection.
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Metadata
Title
Ethmoid glomangioma and oncogenic osteomalacia: a case report
Authors
Camila R. Muniz
Gabriela A. M. Bezerra
Viviane C. da Silva
Priscilla M. F. Aguiar
Gunter Gerson
Catarina B. D’Alva
André A. A. Nunes
Publication date
01-12-2021
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2021
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/s13256-021-02916-0

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