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Published in: Familial Cancer 4/2020

01-10-2020 | Neurofibromatosis | Short Communication

Biallelic NF1 inactivation in high grade serous ovarian cancers from patients with neurofibromatosis type 1

Authors: Eliza Courtney, Sock Hoai Chan, Shao Tzu Li, Diana Ishak, Khurshid Merchant, Tarryn Shaw, Wen Yee Chay, Felicia Hui Xian Chin, Wai Loong Wong, Adele Wong, Joanne Ngeow

Published in: Familial Cancer | Issue 4/2020

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Abstract

Neurofibromatosis type 1 (NF1) is a multisystem disorder caused by germline heterozygous NF1 loss-of-function variants. The NF1 gene encodes neurofibromin, a RAS GTPase-activating protein, which functions by down-regulating RAS/RAF/MAPK-signalling pathways. Somatic NF1 aberrations frequently occur in sporadic ovarian cancer (OC), but the incidence of OC in NF1 patients is rare. Here we report the germline and somatic findings for two unrelated patients with NF1 and high-grade serous OC. Germline testing revealed a heterozygous NF1 pathogenic variant in each patient, c.7096_7101del (p.Asn2366_Phe2367del) and c.964delA (p.Ile322Leufs*54), respectively. No germline variants in well-established OC predisposition genes were detected, including BRCA1 and BRCA2. Tumor loss-of-heterozygosity analysis demonstrated loss of the wild type NF1 allele for both patients. Biallelic NF1 inactivation occurs as part of OC pathogenesis in NF1 patients. Although the penetrance of NF1-associated OC is insufficient to warrant risk-reducing interventions, our findings highlight the potential for therapies targeting the RAS/RAF/MAPK-signalling pathway for these cases.
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Metadata
Title
Biallelic NF1 inactivation in high grade serous ovarian cancers from patients with neurofibromatosis type 1
Authors
Eliza Courtney
Sock Hoai Chan
Shao Tzu Li
Diana Ishak
Khurshid Merchant
Tarryn Shaw
Wen Yee Chay
Felicia Hui Xian Chin
Wai Loong Wong
Adele Wong
Joanne Ngeow
Publication date
01-10-2020
Publisher
Springer Netherlands
Published in
Familial Cancer / Issue 4/2020
Print ISSN: 1389-9600
Electronic ISSN: 1573-7292
DOI
https://doi.org/10.1007/s10689-020-00184-3

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