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Published in: Journal of Medical Case Reports 1/2022

Open Access 01-12-2022 | Vasculitis | Case report

Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report

Authors: Hamed Ghoddusi Johari, Seyed Arman Moein, Saeedeh Shenavande, Armin Amirian, Sara Sadat Nabavizadeh

Published in: Journal of Medical Case Reports | Issue 1/2022

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Abstract

Background

Vascular involvement is an infrequent clinical manifestation of Behçet’s syndrome. Owing to the rarity of arterial involvement in Behçet’s syndrome, there is limited experience in managing this phenomenon.

Case presentation

Here, we report a 28-year-old Iranian man with a Behçet’s syndrome background, who presented with shoulder pain and hoarseness. Chest computed tomography angiography was conducted with a suspicion of a vascular pathology causing pressure on the recurrent laryngeal nerves. The patient was diagnosed with a ruptured innominate artery pseudoaneurysm. An innominate artery to the right common carotid artery bypass was performed, and the pseudoaneurysm was excised and replaced with an expandable polytetrafluoroethylene graft. Eventually, the patient was discharged after an uneventful hospital course.

Conclusion

It appears that we are still a long way from finding the optimal treatment for Behçet’s syndrome vascular involvement, and a combination of surgical and medicinal treatments is required.
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Metadata
Title
Ruptured innominate artery pseudoaneurysm presenting as hoarseness in Behçet’s syndrome: a case report
Authors
Hamed Ghoddusi Johari
Seyed Arman Moein
Saeedeh Shenavande
Armin Amirian
Sara Sadat Nabavizadeh
Publication date
01-12-2022
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2022
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/s13256-022-03662-7

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