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Published in: Journal of Medical Case Reports 1/2022

Open Access 01-12-2022 | Angiography | Case report

Macular telangiectasia with bilateral obliterated capillaries: a case report

Authors: Melika Samadi, Afsaneh Azarkish, Hamid Riazi-Esfahani, Alireza Mahmoudi, Nazanin Ebrahimiadib

Published in: Journal of Medical Case Reports | Issue 1/2022

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Abstract

Background

We report an otherwise healthy adult with macular telangiectasia with aneurysms, ischemia, and obliterated capillaries in both eyes.

Methods

This is a case report with a brief literature review.

Case presentation

A 58-year-old Iranian woman presented with a gradual decrease in vision, with recent deterioration. Past medical history was unremarkable, and best-corrected visual acuity was 3/10 in both eyes. Multimodal imaging including fundus photo, fluorescein angiography, optical coherence tomography, and optical coherence tomography angiography was carried out. In macula of both eyes, parafoveal telangiectasia, occluded vessels, capillary dropouts, and aneurysms were observed. While there were a dense circinate exudation and edema in the macula of the right eye and a thin and disorganized inner retinal layer in the left eye, the outer retina was intact in both eyes. En face optical coherence tomography angiography revealed capillary blunting and rarefaction in both superficial and deep capillary plexuses of retina.

Conclusion

Our case most probably represents a case of type 3 macular telangiectasia in the absence of any systemic association.
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Metadata
Title
Macular telangiectasia with bilateral obliterated capillaries: a case report
Authors
Melika Samadi
Afsaneh Azarkish
Hamid Riazi-Esfahani
Alireza Mahmoudi
Nazanin Ebrahimiadib
Publication date
01-12-2022
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2022
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/s13256-022-03597-z

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