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Published in: Journal of Medical Case Reports 1/2017

Open Access 01-12-2017 | Case report

Congenital basal meningoceles with different outcomes: a case series

Authors: Satomi Okano, Ryosuke Tanaka, Akie Okayama, Etsushi Tsuchida, Fumikatsu Nohara, Nao Suzuki, Toshio Okamoto, Ken Nagaya, Satoru Takahashi, Hiroshi Azuma

Published in: Journal of Medical Case Reports | Issue 1/2017

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Abstract

Background

Basal meningoceles are rare congenital defects and often clinically occult until they result in life-threatening complications. Therefore, it is important to know the diagnostic clues to early diagnosis.

Case presentation

We describe three cases of congenital basal meningocele in a 3-year-old Japanese boy, a 1-month-old Japanese baby boy, and a 10-month-old Japanese baby girl. One of our patients died of sepsis due to traumatic rupture of the meningocele during nasal suction. His meningocele remained undiagnosed until it resulted in the fatal complication. The other patients underwent surgical repair without any complications. Their meningoceles were complicated by midfacial anomalies including cleft palate and hypertelorism, or a sign of nasal obstruction such as snoring.

Conclusions

These clinical features may be a clue to the early diagnosis of congenital basal meningocele, which enables its safe preoperative management and provides an opportunity for surgical repair before the condition results in serious complications.
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Metadata
Title
Congenital basal meningoceles with different outcomes: a case series
Authors
Satomi Okano
Ryosuke Tanaka
Akie Okayama
Etsushi Tsuchida
Fumikatsu Nohara
Nao Suzuki
Toshio Okamoto
Ken Nagaya
Satoru Takahashi
Hiroshi Azuma
Publication date
01-12-2017
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2017
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/s13256-017-1497-7

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