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Published in: Journal of Medical Case Reports 1/2015

Open Access 01-12-2015 | Case report

Red eyes presenting with a fistulous lesion in the left lower extremity: a case report

Authors: Natalia Palmou-Fontana, Enrique Judez Navarro, Oscar Martín Melero, Sergio Losa Palacios

Published in: Journal of Medical Case Reports | Issue 1/2015

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Abstract

Introduction

Very few cases of scar sarcoidosis affecting the eyes and bone together have been reported in the last few years.

Case presentation

We report a case of a 49-year-old Spanish man with recurrent bilateral granulomatous uveitis and a fistulous nodular lesion in the left pre-tibial region (scar granuloma) on the site of an 8-year-old scar. He presented with bilateral hilar adenopathies and elevation of inflammatory markers and angiotensin-converting enzyme. A histologically confirmed sarcoid of the tibia with a radiologic appearance unusual for long tubular bone involvement was observed. He also had bilateral ophthalmologic involvement.

Conclusions

Sarcoidosis is a disease of unknown cause histologically characterized by non-caseating granulomas that can involve any organ or tissue. Osseous sarcoidosis is a relatively rare presentation. However, on the basis of cases reported in the literature, sarcoid lesions on bones are generally asymptomatic. Biologic agents are considered an alternative therapy for sarcoidosis resistant to conventional treatment.
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Metadata
Title
Red eyes presenting with a fistulous lesion in the left lower extremity: a case report
Authors
Natalia Palmou-Fontana
Enrique Judez Navarro
Oscar Martín Melero
Sergio Losa Palacios
Publication date
01-12-2015
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2015
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/s13256-015-0661-1

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