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Published in: Journal of Cardiothoracic Surgery 1/2019

Open Access 01-12-2019 | Dyspnea | Case report

Congenital aneurysmal right coronary artery with a fistula to the left atrium in an adult

Authors: Neerod Kumar Jha, Laszlo Kiraly, Nishant Shah, Arif Al Mulla, Bassem Mora

Published in: Journal of Cardiothoracic Surgery | Issue 1/2019

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Abstract

Background

Congenital coronary artery fistula in association with aneurysm of the involved coronary artery in adults is rare. Moreover, the right coronary artery- left atrial fistula is also uncommon. Most of the cases are asymptomatic. However, symptomatic patients need therapeutic interventions. The potential complications associated with this anomaly are life-threatening, therefore, there is a need to explore more on differential diagnosis, investigations, management strategies and prevention of complications.

Case presentation

We present herewith a 26-year-old male patient with symptoms of chest pain and dyspnea. He was diagnosed with aneurysmal dilatation of the right coronary artery in its entire course which terminated as a fistulous communication into the left atrium. The closure of the fistula was done using autologous pericardial patch under cardiopulmonary bypass. Currently, the patient is being followed up after surgery and receiving anticoagulants.

Conclusion

The advancement in the diagnostic imaging modalities have made it possible to find similar abnormalities more frequently. Due to rare nature of this anomaly, there is a need to explore and discuss management strategies that include medical management, surgical intervention or percutaneous interventions for a successful outcome.
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Metadata
Title
Congenital aneurysmal right coronary artery with a fistula to the left atrium in an adult
Authors
Neerod Kumar Jha
Laszlo Kiraly
Nishant Shah
Arif Al Mulla
Bassem Mora
Publication date
01-12-2019
Publisher
BioMed Central
Published in
Journal of Cardiothoracic Surgery / Issue 1/2019
Electronic ISSN: 1749-8090
DOI
https://doi.org/10.1186/s13019-019-0854-6

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