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BMC Musculoskeletal Disorders
Published in: BMC Musculoskeletal Disorders 1/2019

Open Access 01-12-2019 | Bone Defect | Case report

Gorham’s disease: treatment with an autologous iliac bone graft and a reverse total shoulder arthroplasty

Authors: Linjie Feng, Yaoping Wu, Xiangqian Yu, Wenguo Zhao

Published in: BMC Musculoskeletal Disorders | Issue 1/2019

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Abstract

Background

Gorham’s disease (GSD) is a rare osteolytic disease with unclear etiology, and no known prevention or effective treatment. Here we report a new surgical treatment for a case of GSD in September 2017.

Case presentation

We report GSD in a 52-year-old woman. She had disappearance of her humeral head and a defect of the glenoid bone in her left shoulder joint, which were serious obstacles to joint function. We used an autologous iliac bone graft to repair the glenoid bone defect and a reverse total shoulder arthroplasty. After surgery, humeral osteolysis did not continue, and her shoulder function recovered well.

Conclusions

This case suggests that autologous bone grafting can still be used to treat GSD despite it being an osteolytic disease. The successful treatment suggests that this method could be used for GSD in other bones.
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Metadata
Title
Gorham’s disease: treatment with an autologous iliac bone graft and a reverse total shoulder arthroplasty
Authors
Linjie Feng
Yaoping Wu
Xiangqian Yu
Wenguo Zhao
Publication date
01-12-2019
Publisher
BioMed Central
Keyword
Bone Defect
Published in
BMC Musculoskeletal Disorders / Issue 1/2019
Electronic ISSN: 1471-2474
DOI
https://doi.org/10.1186/s12891-019-2436-0

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