Top

Journal of Medical Case Reports

Published in:

Open Access 01-12-2014 | Case report

Anomalous origin of the left coronary artery from the pulmonary artery presenting as dilated cardiomyopathy: a case report

Authors: Rym Gribaa, Mehdi Slim, Helmi Ben Salem, Elyes Neffati, Essia Boughzela

Published in: Journal of Medical Case Reports | Issue 1/2014

Abstract

Introduction

Anomalous origin of the left coronary artery from the pulmonary artery is a rare congenital anomaly and one of the causes of myocardial ischemia. The usual clinical course is severe left-sided heart failure and mitral valve insufficiency presenting during the first months of life.

Case presentation

We report the case of a 6-month-old Tunisian girl who presented with dilated cardiomyopathy. Echocardiography suspected anomalous origin of the left coronary artery. The definitive diagnosis of anomalous origin of the left coronary artery from the pulmonary artery was reached by multislice computed tomography and coronary angiography.

Conclusion

In cases of dilated cardiomyopathy, anomalous origin of the left coronary artery from the pulmonary artery syndrome has to be kept in mind as a surgically correctable cause.

Available only for authorised users

Erdinc M, Hosgor K, Karahan O: Repair of anomalous origin of the left coronary artery arising from right pulmonary artery with rolled-conduit-extended reimplantation in an adult. J Card Surg. 2011, 26: 604-607.CrossRefPubMed

Wollenek G, Domanig E, Salzer-Muhar U, Havel M, Wimmer M, Wolner E: Anomalous origin of the left coronary artery: a review of surgical management in 13 patients. J Cardiovasc Surg (Torino). 1993, 34: 399-405.

Brooks HS: Two cases of an abnormal coronary artery of the heart arising from the pulmonary artery: with some remarks upon the effect of this anomaly in producing cirsoid dilatation of the vessels. J Anat Physiol. 1885, 20: 26-29.PubMedPubMedCentral

Wilson CL, Dlabal PW, Holeyfield RW, Akins CW, Knauf DG: Anomalous origin of left coronary artery from pulmonary artery. Case report and review of literature concerning teen-agers and adults. J Thorac Cardiovasc Surg. 1977, 73: 887-893.PubMed

Bland EF, White PD, Garland J: Congenital anomalies of the coronary arteries: Report of an unusual case associated with cardiac hypertrophy. Am Heart J. 1933, 8: 787-801.CrossRef

Fierens C, Budts W, Denef B, Van De Werf F: A 72 year old woman with ALCAPA. Heart. 2000, 83: E2-CrossRefPubMedPubMedCentral

Takimura CK, Nakamoto A, Hotta VT, Campos MF, Malamo M, Otsubo R: Anomalous origin of the left coronary artery from the pulmonary artery: report of an adult case. Arq Bras Cardiol. 2002, 78: 309-314.CrossRefPubMed

Barbetakis N, Efstathiou A, Efstathiou N, Papagiannopoulou P, Soulountsi V, Fessatidis I: A long-term survivor of Bland-White-Garland syndrome with systemic collateral supply: a case report and review of the literature. BMC Surg. 2005, 5: 23-CrossRefPubMedPubMedCentral

Johnsrude CL, Perry JC, Cecchin F, Smith EO, Fraley K, Friedman RA, Towbin JA: Differentiating anomalous left main coronary artery originating from the pulmonary artery in infants from myocarditis and dilated cardiomyopathy by electrocardiogram. Am J Cardiol. 1995, 75: 71-74.CrossRefPubMed

10.

Hoffman JI: Electrocardiogram of anomalous left coronary artery from the pulmonary artery in infants. Pediatr Cardiol. 2013, 34: 489-491.CrossRefPubMed

11.

Sanjay T, Apurba KS, Kurur SV: Lessons from a case of anomalous the left coronary artery from the pulmonary artery. Ind J Thorac Cardiovasc Surg. 2005, 21: 171-172.CrossRef

12.

Nacif MS, Luz JH, Moreira DM, Rochitte CE, Oliveira Júnior AC: Anomalous origin of Coronary Artery (ALCAPA) in 64-channel TC scanner. Arq Bras Cardiol. 2010, 94: 143-146.CrossRefPubMed

13.

Yau JM, Singh R, Halpern EJ, Fischman D: Anomalous origin of the left coronary artery from the pulmonary artery in adults: a comprehensive review of 151 adult cases and a new diagnosis in a 53-year-old woman. Clin Cardiol. 2011, 34: 204-210.CrossRefPubMed

14.

Takeuchi S, Imamura H, Katsumoto K, Hayashi I, Katohgi T, Yozu R, Ohkura M, Inoue T: New surgical method for repair of anomalous left coronary artery from pulmonary artery. J Thorac Cardiovasc Surg. 1979, 78: 7-11.PubMed

Title: Anomalous origin of the left coronary artery from the pulmonary artery presenting as dilated cardiomyopathy: a case report
Authors: Rym Gribaa
Mehdi Slim
Helmi Ben Salem
Elyes Neffati
Essia Boughzela
Publication date: 01-12-2014
Publisher: BioMed Central
Published in: Journal of Medical Case Reports / Issue 1/2014
Electronic ISSN: 1752-1947
DOI: https://doi.org/10.1186/1752-1947-8-170

At a glance: The ONWARDS insulin icodec trials

Springer Medicine

Anomalous origin of the left coronary artery from the pulmonary artery presenting as dilated cardiomyopathy: a case report

Abstract

Introduction

Case presentation

Conclusion

At a glance: The ONWARDS insulin icodec trials

Springer Medicine

Abstract

Introduction

Case presentation

Conclusion

Please log in to get access to this content

Other articles of this Issue 1/2014

Bowel obstruction caused by an internal hernia that developed after laparoscopic subtotal colectomy: a case report

Recurrent vitreous hemorrhage associated with regressed retinopathy of prematurity in a 47-year-old patient: a case report

Multiple congenital granular cell epulis in a female newborn: a case report

Treatment decisions in a man with Hodgkin lymphoma and Guillian-Barré syndrome: a case report

Posterior reversible encephalopathy syndrome after depletive lumbar puncture: a case report

Subchondral fracture of the femoral head after acetabular fracture: a case report