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Published in: Journal of Medical Case Reports 1/2011

Open Access 01-12-2011 | Case report

Lingual juvenile xanthogranuloma in a woman: a case report

Authors: Alessandro Villa, Umberto Mariani, Francesco Villa

Published in: Journal of Medical Case Reports | Issue 1/2011

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Abstract

Introduction

Juvenile xanthogranuloma is a rare non-Langerhans cell histiocytosis that usually occurs during infancy and early childhood. The presence of single or multiple raised cutaneous lesions characterize this self-healing disorder. Extracutaneous sites are rare.

Case presentation

We present a rare case of oral juvenile xanthogranuloma in a 49-year-old Caucasian woman. The histopathologic diagnosis of the lingual neoformation was histiocitary proliferation with the presence of giant cells, Touton type, compatible with juvenile xanthogranuloma.

Conclusion

To establish an accurate diagnosis, microscopic evaluation and immunohistochemical staining are necessary. Dentists, dermatologists and general practitioners may be the first to recognize this rare condition during the inspection of the oral cavity.
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Metadata
Title
Lingual juvenile xanthogranuloma in a woman: a case report
Authors
Alessandro Villa
Umberto Mariani
Francesco Villa
Publication date
01-12-2011
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2011
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/1752-1947-5-30

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