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Journal of Medical Case Reports
Published in: Journal of Medical Case Reports 1/2010

Open Access 01-12-2010 | Case report

A neonate with left pulmonary artery thrombosis and left lung hypoplasia: a case report

Authors: Nahed O ElHassan, Christi Sproles, Ritu Sachdeva, Sadaf T Bhutta, Joanne S Szabo

Published in: Journal of Medical Case Reports | Issue 1/2010

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Abstract

Introduction

Spontaneous intrauterine arterial thrombosis and congenital pulmonary hypoplasia are rare conditions and have not been reported to occur together. The literature rather includes two reports of babies with neonatal pulmonary artery occlusion and post-infarction cysts of the lungs.

Case presentation

We report a case of a live Caucasian male newborn with left lung hypoplasia that occurred in association with left pulmonary artery thrombosis. Despite a critical neonatal course, including extracorporeal membrane oxygenation, this infant is alive and well at 18 months of age without any neurodevelopmental sequelae or reactive airway disease.

Conclusion

This association suggests the possibility of an intrauterine vascular event between the fifth and eighth weeks of gestation during early pulmonary artery and lung development.
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Metadata
Title
A neonate with left pulmonary artery thrombosis and left lung hypoplasia: a case report
Authors
Nahed O ElHassan
Christi Sproles
Ritu Sachdeva
Sadaf T Bhutta
Joanne S Szabo
Publication date
01-12-2010
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2010
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/1752-1947-4-284

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