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Published in: Journal of Medical Case Reports 1/2009

Open Access 01-12-2009 | Case report

Tracheal agenesis as a rare cause of difficult intubation in a newborn with respiratory distress: a case report

Authors: Raja Ahmad, Kahairi Abdullah, Lukman Mokhtar, Ahmad Fadzil

Published in: Journal of Medical Case Reports | Issue 1/2009

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Abstract

Introduction

Tracheal agenesis is a very rare congenital airway anomaly. It may pose a great challenge to the first attending physician both in diagnosis and in establishing the airway during the first day of life.

Case presentation

We report a newborn Malay baby boy with trachea agenesis (type III by Floyd's classification) who presented with severe respiratory distress immediately after birth. Clinical diagnosis in this case was not straightforward, as it started with difficulty in intubation followed by an unsuccessful emergency tracheostomy in the neonatal intensive care unit. Urgent surgical neck exploration with endoscopic examination in the general operating theatre revealed the final diagnosis. The authors present a short description of the embryopathology and diagnostic criteria of the abnormality.

Conclusion

We hope this case presentation will be valuable in increasing the awareness of physicians about this rare cause of tracheal obstruction or difficult intubation.
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Metadata
Title
Tracheal agenesis as a rare cause of difficult intubation in a newborn with respiratory distress: a case report
Authors
Raja Ahmad
Kahairi Abdullah
Lukman Mokhtar
Ahmad Fadzil
Publication date
01-12-2009
Publisher
BioMed Central
Published in
Journal of Medical Case Reports / Issue 1/2009
Electronic ISSN: 1752-1947
DOI
https://doi.org/10.1186/1752-1947-3-105

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