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Published in: Italian Journal of Pediatrics 1/2013

Open Access 01-12-2013 | Letter to the Editor

Home treatment in paediatric patients with Hunter syndrome: the first Italian experience

Authors: Ferdinando Ceravolo, Italia Mascaro, Simona Sestito, Elisa Pascale, Antonino Lauricella, Elio Dizione, Daniela Concolino

Published in: Italian Journal of Pediatrics | Issue 1/2013

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Abstract

Hunter syndrome (mucopolysaccharidosis type II [MPS II], OMIM309900) is a rare X-linked lysosomal storage disorder caused by the deficiency of the enzyme iduronate-2-sulphatase, resulting in accumulation of glycosaminoglycans, progressive multisystem organ failure, and early death. Enzyme replacement therapy (ERT) with weekly intravenous infusions of idursulfase, a treatment for MPS II and commercially available since 2007, has been shown to improve certain symptoms and signs of the disease. The efficacy and safety data of this enzyme preparation have been widely reported and, after a change to the idursulfase Summary of Product Characteristics in March 2010, home ERT by infusion is now an option for selected patients. Previously reported experiences of home therapy in MPS II have shown increased treatment compliance and an improvement in quality of life for both patients and families. We report the results of the home therapy experience of 3 paediatric patients with MPS II in southern Italy. This pilot experience with home infusion is the first reported from Italy.
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Metadata
Title
Home treatment in paediatric patients with Hunter syndrome: the first Italian experience
Authors
Ferdinando Ceravolo
Italia Mascaro
Simona Sestito
Elisa Pascale
Antonino Lauricella
Elio Dizione
Daniela Concolino
Publication date
01-12-2013
Publisher
BioMed Central
Published in
Italian Journal of Pediatrics / Issue 1/2013
Electronic ISSN: 1824-7288
DOI
https://doi.org/10.1186/1824-7288-39-53

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