Skip to main content
Top
Published in: Indian Journal of Otolaryngology and Head & Neck Surgery 2/2022

02-08-2020 | Clinical Report

Unusual Cause of Neonatal Stertor

Authors: Sophia Amalanathan, Suma Susan Mathews, V. Rupa

Published in: Indian Journal of Otolaryngology and Head & Neck Surgery | Special Issue 2/2022

Login to get access

Abstract

We report a case of neonatal respiratory distress caused by an epignathus. This rare tumour, arising from the basisphenoid and protruding from the mouth, is associated with high perinatal mortality. We highlight unique clinico-radiological findings and multidisciplinary approach for a successful outcome. We review oropharyngeal teratomas reported in the literature with current management approaches.
Literature
1.
go back to reference Oliveira-Filho AG, Carvalho MH, Bustorff-Silva JM, Sbragia-Neto L, Miyabara S, Oliveira ER (1998) Epignathus: report of a case with successful outcome. J Pediatr Surg 33:520–521CrossRefPubMed Oliveira-Filho AG, Carvalho MH, Bustorff-Silva JM, Sbragia-Neto L, Miyabara S, Oliveira ER (1998) Epignathus: report of a case with successful outcome. J Pediatr Surg 33:520–521CrossRefPubMed
2.
go back to reference Chaudhry AP, Loré JM, Fisher JE, Gambrino AG (1978) So-called hairy polyps or teratoid tumors of the nasopharynx. Arch Otolaryngol 104:517–525CrossRefPubMed Chaudhry AP, Loré JM, Fisher JE, Gambrino AG (1978) So-called hairy polyps or teratoid tumors of the nasopharynx. Arch Otolaryngol 104:517–525CrossRefPubMed
3.
go back to reference Cay A, Bektas D, Imamoglu M, Bahadir O, Cobanoglu U, Sarihan H (2004) Oral teratoma: a case report and literature review. Pediatr Surg Int 20:304–308CrossRefPubMed Cay A, Bektas D, Imamoglu M, Bahadir O, Cobanoglu U, Sarihan H (2004) Oral teratoma: a case report and literature review. Pediatr Surg Int 20:304–308CrossRefPubMed
4.
go back to reference Vandenhaute B, Leteurtre E, Lecomte-Houcke M, Pellerin P, Nuyts JP, Cuisset JM et al (2000) Epignathus teratoma: report of three cases with a review of the literature. Cleft Palate Craniofac J 37:83–91CrossRefPubMed Vandenhaute B, Leteurtre E, Lecomte-Houcke M, Pellerin P, Nuyts JP, Cuisset JM et al (2000) Epignathus teratoma: report of three cases with a review of the literature. Cleft Palate Craniofac J 37:83–91CrossRefPubMed
5.
go back to reference Sauter ER, Diaz JH, Arensman RM, Butcher RB, Guarisco JL, Hayes DH (1990) The perioperative management of neonates with congenital oropharyngeal teratomas. J Pediatr Surg 25(9):925–928CrossRefPubMed Sauter ER, Diaz JH, Arensman RM, Butcher RB, Guarisco JL, Hayes DH (1990) The perioperative management of neonates with congenital oropharyngeal teratomas. J Pediatr Surg 25(9):925–928CrossRefPubMed
6.
go back to reference Clement K, Chamberlain P, Boyd P, Molyneux A (2001) Prenatal diagnosis of an epignathus: a case report and review of the literature. Ultrasound Obstet Gynecol 18:178–181CrossRefPubMed Clement K, Chamberlain P, Boyd P, Molyneux A (2001) Prenatal diagnosis of an epignathus: a case report and review of the literature. Ultrasound Obstet Gynecol 18:178–181CrossRefPubMed
7.
go back to reference Carvalho CHP, Nonaka CFW, Elias CTV, Matheus RCS, Dias RMB, Souza LB et al (2017) Giant epignathus teratoma discovered at birth: a case report and 7-year follow-up. Braz Dent J 28:256–261CrossRefPubMed Carvalho CHP, Nonaka CFW, Elias CTV, Matheus RCS, Dias RMB, Souza LB et al (2017) Giant epignathus teratoma discovered at birth: a case report and 7-year follow-up. Braz Dent J 28:256–261CrossRefPubMed
8.
go back to reference Moreddu E, Pereira J, Vaz R, Lena G, Triglia J-M, Nicollas R (2015) Combined endonasal and neurosurgical resection of a congenital teratoma with pharyngeal, intracranial and orbital extension: case report, surgical technique and review of the literature. Int J Pediatr Otorhinolaryngol 79:1991–1994CrossRefPubMed Moreddu E, Pereira J, Vaz R, Lena G, Triglia J-M, Nicollas R (2015) Combined endonasal and neurosurgical resection of a congenital teratoma with pharyngeal, intracranial and orbital extension: case report, surgical technique and review of the literature. Int J Pediatr Otorhinolaryngol 79:1991–1994CrossRefPubMed
9.
go back to reference Zia-Ul-Miraj Ahmad M, Brereton RJ, Madden NP (1996) Oronasopharyngeal teratomas. Pediatr Surg Int 11:203–205CrossRefPubMed Zia-Ul-Miraj Ahmad M, Brereton RJ, Madden NP (1996) Oronasopharyngeal teratomas. Pediatr Surg Int 11:203–205CrossRefPubMed
10.
go back to reference Tsai YT, Cala-Or MA, Lui CC, Wang TJ, Lai JP (2013) Epignathus teratoma with duplication of mandible and tongue: report of a case. Cleft Palate Craniofac J 50:363–368CrossRefPubMed Tsai YT, Cala-Or MA, Lui CC, Wang TJ, Lai JP (2013) Epignathus teratoma with duplication of mandible and tongue: report of a case. Cleft Palate Craniofac J 50:363–368CrossRefPubMed
Metadata
Title
Unusual Cause of Neonatal Stertor
Authors
Sophia Amalanathan
Suma Susan Mathews
V. Rupa
Publication date
02-08-2020
Publisher
Springer India
Published in
Indian Journal of Otolaryngology and Head & Neck Surgery / Issue Special Issue 2/2022
Print ISSN: 2231-3796
Electronic ISSN: 0973-7707
DOI
https://doi.org/10.1007/s12070-020-02010-9

Other articles of this Special Issue 2/2022

Indian Journal of Otolaryngology and Head & Neck Surgery 2/2022 Go to the issue