We describe a patient who presented with dystonia of her small finger secondary to entrapment neuropathy of the ulnar nerve at the elbow. Pre operative electrophysiological studies suggested that the locus of entrapment was located proximal to the medial epicondyle. This was confirmed intraoperatively by the presence of a thickened and prominent arcade of Struthers. Surgical decompression resulted in a rapid and dramatic improvement of the dystonic pattern as well as an improvement in nerve conduction. A review of literature has not revealed any other reports of such a clear cut association between ulnar nerve entrapment and non task-specific focal hand dystonia.