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Published in: BMC Gastroenterology 1/2021

Open Access 01-12-2021 | Esophageal Rupture | Case report

Endoluminal vacuum therapy in the management of an esophago-pleural fistula as a complication of Boerhaave syndrome in a patient with eosinophilic esophagitis

Authors: Carlos Tuñon, Juan De Lucas, Jan Cubilla, Rafael Andrade, Miguel Aguirre, Julio Zúñiga Cisneros

Published in: BMC Gastroenterology | Issue 1/2021

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Abstract

Background

Boerhaave syndrome is an uncommon condition that represents about 15% of all esophageal perforation. A subset of these patients has eosinophilic esophagitis, a chronic inflammatory disease of the esophagus, that carries a risk of perforation of about 2%. Esophageal perforations can rarely result in the development of an esophago-pleural fistula. Treatment of esophago-pleural fistula represent a challenge due to lack of high quality evidence and scarce reported experience. Endoluminal vacuum-assisted therapy could have a role in the management by using the same principle applied in external wounds which provide wound drainage and tissue granulation.

Case presentation

We report a unique case of a 24-year-old man with eosinophilic esophagitis complicated with an esophageal rupture who developed an esophago-pleural fistula and was successfully managed with a non-surgical approach using endoluminal vacuum-assisted therapy. To our knowledge this could be the first experience reported in a patient with eosinophilic esophagitis.

Conclusion

Endoluminal vacuum-assisted therapy might be an effective and novel strategy in patients with eosinophilic esophagitis and esophago-pleural fistula as a consequence of Boerhaave syndrome. Appropriately designed studies are required.
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Metadata
Title
Endoluminal vacuum therapy in the management of an esophago-pleural fistula as a complication of Boerhaave syndrome in a patient with eosinophilic esophagitis
Authors
Carlos Tuñon
Juan De Lucas
Jan Cubilla
Rafael Andrade
Miguel Aguirre
Julio Zúñiga Cisneros
Publication date
01-12-2021
Publisher
BioMed Central
Published in
BMC Gastroenterology / Issue 1/2021
Electronic ISSN: 1471-230X
DOI
https://doi.org/10.1186/s12876-021-02058-z

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