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Published in: Journal of Cardiothoracic Surgery 1/2019

Open Access 01-12-2019 | Congenital Heart Anomaly | Case report

Single-stage hybrid repair of a ruptured Kommerell diverticulum associated with dextrorotation, bovine arch, and bicuspid aortic valve

Authors: Jeko M. Madjarov, Michael G. Katz, Sarah M. Gubara, Svetozar Madzharov, Kevin Reames, Sophia Madjarova, Francis Robicsek

Published in: Journal of Cardiothoracic Surgery | Issue 1/2019

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Abstract

Background

A strategy for the surgical repair of ruptured Kommerell diverticulum has not yet been established. The aim of this study is to demonstrate that this entity could be associated with a number of other cardiac anomalies and this lesion can be successfully treated by a hybrid approach.

Case presentation

The patient, with a combination of ruptured Kommerell diverticulum, dextrorotation, bovine arch, and bicuspid aortic valve, underwent emergency surgery. A single stage hybrid surgical/endovascular repair including subclavian artery revascularization, aortic resection with open proximal anastomosis under circulatory arrest, endovascular stenting, and valve repair was performed. Histological studies indicated the presence of the aortic wall media degeneration. Postoperative course was uneventful and patient is free of symptoms during 2-year follow up.

Conclusions

Less invasive hybrid technique is safe and effective treatment option. Accumulated knowledge of Kommerell diverticulum has lead to understanding the best clinical treatment for this complicated aortic anomaly.
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Metadata
Title
Single-stage hybrid repair of a ruptured Kommerell diverticulum associated with dextrorotation, bovine arch, and bicuspid aortic valve
Authors
Jeko M. Madjarov
Michael G. Katz
Sarah M. Gubara
Svetozar Madzharov
Kevin Reames
Sophia Madjarova
Francis Robicsek
Publication date
01-12-2019
Publisher
BioMed Central
Published in
Journal of Cardiothoracic Surgery / Issue 1/2019
Electronic ISSN: 1749-8090
DOI
https://doi.org/10.1186/s13019-019-0942-7

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