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Published in: Italian Journal of Pediatrics 1/2012

Open Access 01-12-2012 | Case report

Cardiac valve disease: an unreported feature in Ehlers Danlos syndrome arthrocalasia type?

Authors: Daniela Melis, Gerarda Cappuccio, Virginia Maria Ginocchio, Giorgia Minopoli, Maurizia Valli, Massimiliano Corradi, Generoso Andria

Published in: Italian Journal of Pediatrics | Issue 1/2012

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Abstract

Ehlers Danlos syndrome (EDS) athrocalasia type (type VII), is characterized by joint hypermobility, skin hyperextensibility and tissue fragility. No heart involvement has been reported. Two forms have been described: type VII A and VII B. The abnormally processed collagen α2(I) and the skipping of the exon 6 in COL1A2 gene are typically detected in EDS type VII B. We describe a seven-year old female, with a phenotype consistent with EDS type VII B and a diagnosis further confirmed by biochemical and molecular analyses. Cardiac ultrasound showed normal data in the first year of life. When she was 5 years old, the patient developed mitral valve regurgitation, and aortic and tricuspidal insufficiency at 7 years of age. To our knowledge, this is the first report of cardiac valvular involvement in EDS VII B. This feature probably has been underreported for the limited follow-up of the patients. Echocardiography might be warranted in the clinical assessment of EDS VII patients.
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Metadata
Title
Cardiac valve disease: an unreported feature in Ehlers Danlos syndrome arthrocalasia type?
Authors
Daniela Melis
Gerarda Cappuccio
Virginia Maria Ginocchio
Giorgia Minopoli
Maurizia Valli
Massimiliano Corradi
Generoso Andria
Publication date
01-12-2012
Publisher
BioMed Central
Published in
Italian Journal of Pediatrics / Issue 1/2012
Electronic ISSN: 1824-7288
DOI
https://doi.org/10.1186/1824-7288-38-65

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